Huang · Developmental cell 2014 · Preclinical animal and in vitro mechanistic study · n=?

Developmental and activity-dependent expression of LanCL1 confers antioxidant activity required for neuronal survival.

Cited 63 times in the scientific literature.

Level 5 - mechanism / opinion, no new human data

Bench and animal research with no human clinical data

PubMed 25158856 · doi:10.1016/j.devcel.2014.06.011 · record verified 2026-08-30

What was done

The authors investigated the expression, regulation, and functional role of the brain-enriched antioxidant gene LanCL1. They evaluated LanCL1 expression patterns across development and in response to neuronal activity, neurotrophic factors, and oxidative stress. Using genetic deletion models, transgenic expression, and in vitro enzymatic assays with purified eukaryotic LanCL1 protein, they evaluated reactive oxygen species (ROS) accumulation, cellular damage, mitochondrial function, neurodegeneration, and catalytic activity.

What was found

LanCL1 was found to be enriched in neurons, developmentally regulated, and induced by neuronal activity, neurotrophic factors, and oxidative stress. Genetic deletion of LanCL1 increased ROS accumulation in the brain, accompanied by development-related lipid, protein, and DNA damage, mitochondrial dysfunction, and apoptotic neurodegeneration. Transgenic expression of LanCL1 protected neurons from ROS. Purified LanCL1 catalyzed the formation of thioether products similar to glutathione S-transferase. No specific numerical values were reported in the abstract.

Why it matters

The findings identify LanCL1 as an activity-dependent, neuron-specific glutathione defense mechanism essential for protecting developing and active neurons against oxidative damage and degeneration.

Limits

The abstract provides only qualitative findings without quantitative measurements, effect sizes, or sample sizes. The work relies on preclinical cell and animal models, and findings may not fully capture human neurobiology or clinical pathology.

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