Sabatino · Molecular therapy : the journal of the American Society of Gene Therapy 2022 · expert roundtable / narrative review · n=?

Evaluating the state of the science for adeno-associated virus integration: An integrated perspective.

Cited 209 times in the scientific literature.

Level 5 - mechanism / opinion, no new human data

Narrative review and expert roundtable white paper without original human data or systematic review methodology

PubMed 35690906 · doi:10.1016/j.ymthe.2022.06.004 · record verified 2026-08-28

What was done

This white paper summarizes discussions from a virtual roundtable hosted by the American Society of Gene and Cell Therapy (ASGCT) on August 18, 2021. Preclinical and clinical experts reviewed evidence of recombinant adeno-associated virus (rAAV) host genome integration, risks of insertional mutagenesis in patients, technical considerations, regulatory guidance, and bioethics.

What was found

No numerical data or rates are reported in the abstract. Most rAAV DNA remains episomal, though low-frequency genomic integration occurs. Although rAAV insertional mutagenesis has caused tumorigenesis in a small number of neonatal mouse studies, oncogenesis risk in humans remains theoretical with no confirmed genotoxic events reported to date.

Why it matters

As rAAV gene therapies expand clinically, this paper contextualizes theoretical genotoxicity and insertional mutagenesis risks to inform research design, regulatory policy, and patient care.

Limits

This is a narrative expert review rather than a systematic review. The abstract provides no quantitative integration frequencies. Tumorigenesis data are derived entirely from preclinical neonatal mouse models, and true human clinical risk remains theoretical and unquantified.

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